A 2-month-old boy who had abnormal elevation of the tongue and some difficulty in swallowing, was first sent to our clinic on June 20, 1979. Examination revealed a cystic mass at the midline of the mouth floor, where the cyst considerably raised his tongue superiorly. This cystic lesion was entirely removed by blunt dissection on July 6. His deglutition improved immediately after awaking from general anesthesia for the surgery.
The cyst measured approximately 3 × 2 × 1cm and had a thick fibrous capsule. Histologically, the cyst had a slender lumen lined by the small intestinal tract layers such as typical intestinal villi, Lieberkühn's glands, Paneth's cells, goblet cells and the intestinal musculature. Furthermore, underneath the small intestinal layers, there was the pancreatic tissue characterized by typical zymogen-rich glandular structure containing scattered Langerhans' islets.
According to the Authors' review of the world literature, there was no such a case report of the oral heterotopic or choristomatic cyst containing both the intestinal tract and the pancreatic tissues, although there were approximately 20 case reports on the heterotopic oral cysts containing merely gastric or intestinal mucosa.
