Pleomorphic adenoma is said to frequently occur in the parotid gland but in general is relatively rare in the other salivary gland. However, the site of appearance and its frequency vary in the literatures concerned and the occurrence from the small salivary gland is reported to be very high in Japan. Recently, we experienced a case of benign pleomorphic adenoma of the left submandibular gland in origin in a 44 year old woman. The patient was aware of swelling of the left submandibular gland for 5 years without any treatment but recently visited our department because of increased radiating pain. Atpalpation, an immobile, elastically hard tumor of a pigeon egg size with clearly cut off margin was felt on the left submandibular gland. After the diagnosis of salivary gland tumor, the tumor including submandibular gland was removed. On the eighth months after operation, prognosis is favorable but the course will be further observed considering possible recurrence and malignant changes.