Verruciform Xanthoma with histopathological characteristics of verruciform growth and the proliferation of xanthoma cell in the lamina propria was first described in 1971 by Shafer as Histiocytosis-Y. Though occasionally reported later in occidental countries, this disease is relatively rare. Especially in Japan this disease is rarely documented. The gingiva is a common site of occurrence. Those occurring in the tongue or buccal mucosa are very rare. Recently we encountered a 64-year-old woman with this disease in the left lateral margin of the tongue.
