This paper reports a rare case of odonto-ameloblastoma in the mandible. A 61-year-old male patient had felt a painless bony swelling in the right mandibular molar region. Roentgenographic examination revealed a hen egg-sized, multilocular radiolucent area with two radiopaque masses extending from the right mandibular first molar to the mandibular ramus. It was histologically diagnosed to be an ameloblastoma by biopsy.
The patient was treated by segmental mandibulectomy and iliac bone grafting for reconstruction. Histopathological examination of the resected specimen revealed a mixture of hard tissues composed of immature dentin, enamel and cementum adjacent to the tumor nest of the ameloblastoma, arising in the cyst wall and subepithelial connective tissue. Therefore, the lesion was finally diagnosed to be an odontoameloblastoma.
There have been no sign of tumor recurrence at 1 year and 8 months postoperatively.