Abstract
We report a rare case of Onodi cell mucocele. The patient was a 37-year-old man who developed acute impairment of his left visual acuity without pain or abnormal findings in the ocular fundus. Bone window CT scan and MR images demonstrated a mass lesion surrounding and over the left optic canal. An emergency craniotomy revealed an Onodi cell mucocele, and its excision resulted in good visual recovery for the patient. Onodi cells are the most posterior air cells of the ethmoid sinus. They are anatomically situated over the optic canal. Onodi cell mucocele must be included in the differential diagnosis of unilateral retrobulbar optic neuropathy. Careful examination of CT scans and MR images, and prompt surgical intervention are recommended.