2016 Volume 62 Issue 7 Pages 346-351
Arteriovenous malformation (AVM) is rare in the oral and maxillofacial region, and it is often difficult to manage associated hemorrhage. We report a case of broad AVM in the maxillofacial region that occurred suddenly and was associated with frequent intraoral hemorrhages on the eruption of milk teeth and threatened the patient’s life.
A 2-month-old boy was referred to our hospital because of mandibular swelling. Computed tomography and magnetic resonance imaging revealed an AVM extending from the mandible to the oral floor and tongue. Arterial hemorrhages from the gingiva had been recognized from 8 months of age, and treatment by embolization had been done 9 times between the ages of 8 months and 2 years 10 months. Because hemorrhages were not controlled by embolization, we directly injected cyanoacrylate into the AVM from the age of 2 years 10 months to 7 years. The patient has been treated through 21 admissions since 8 months of age, and the AVM of mandibular bone disappeared at 7 years of age. When the patient was 18 years old, the AVM was not recognized in the mandibular bone, but it was found in soft tissue from the mental to submandibular region.