A Case of Intususseption Caused by Pneumatosis Cystoides Intestinalis in a 17-year-old Man

Abstract

A 17-year-old man presented with intensifying abdominal pain which occurred on the day before. Abdominal CT findings showed intussusception caused by a mass lesion in the ileocecal region. High-pressure enema performed for diagnosis and therapy was unsuccessful and we could not reduce the intussusception. Therefore, emergency operation was performed. Surgical findings confirmed intussusception in the transverse colon, which was arising from the ascending colon, cecum and ileum. After manual reduction of the intussusception, we could not completely exclude a possibility of malignant tumor. Accordingly, we performed ileocecal resection. Pathological examination revealed that the tumor was pneumatosis cystoides intestinalis (PCI). PCI is a comparatively rare disease that produces a large number of aerobic cyst under the submucosal or subserosal structures of the digestive tract wall. Few studies have reported intussusception with PCI. We report this case with some literature review.