Abstract
Anterior urethral valve and diverticulum are rare lesions and only 21 and 45 pediatric cases, respectively, were reported in Japan. However, pediatric cases may be missed when micturtion is less affected and/or systemic urological examination including the urethra is not performed. The lesions, if untreated, cause renal dysfunction due to secondary hydronephrosis and urinary infection. Therefore, they should be taken into consideration in differential diagnosis of dysuria in children. We recently encountered an infant with anterior urethral valve and diverticulum, who was successfully treated by urethral reconstruction on the 54th day of age following an initial cystostomy in neonatal period. In this case report, symptoms, complications, diagnosis and treatment of the lesions are described.