Antenatally Diagnosed and Asymptomatic Cases of Congenital Cystic Adenomatoid Malformation: A Report of Two Cases That Imply the Importance of the Optimal Timing of Surgery

Abstract

We report two cases of congenital cystic adenomatoid malformation (CCAM). Case 1: a prenatal sonographic examination revealed a left intrathoracic cyst. A male baby weighing 3,452 g was born at 37 weeks of gestation and was diagnosed as having CCAM Stocker type 1. He was asymptomatic in the neonatal period, but was hospitalized with a cyst infection at 3 months of age. Left lower lobectomy was performed at 6 months of age. The intraoperative findings showed pleural adhesion due to the infection. Case 2: a prenatal sonographic examination revealed bilateral intrathoracic cysts. A female baby weighing 2,128 g was born at 36 weeks of gestation and was diagnosed as having bilateral CCAM Stocker type 1 involving the posterior segment of the right lung and the lower lobe of the left lung. She was asymptomatic in the neonatal period and underwent left lower lobectomy at 11 months of age and right upper lobectomy at 14 months of age without infection. Surgery is advantageous in CCAM patients without previous infections, especially bilateral cases. The absence of previous infections helps in ensuring the safety of surgery and a good postoperative lung function. She gained weight after surgery, so we recognized the necessity of early surgery to improve growth disorders.