We report a case of a 30-year-old man with multiple hemangiomas of the skin distributed in a unilateral pattern. He first noticed a nodule on his right sole at the age of 10 years old. On physical examination, CT scanning and MRI revealed six deep dermal or subcutaneous nodules which were lecated on the right side of his neck, shoulder, finger, chest, back and sole. No hemangioma in any of his internal organs was detected. The histopathological findings of the nodules showed irregularly dilated and variously-sized vascular spaces in the lower dermis. These findings were the same as those of cavernous hemangioma. In addition, smooth muscles and eccrine sweat glands were present close to the dilated vascular spaces. Our case is similar to the one reported by Wilkin in 1980, named unilateral dermatomal cavernous hemangiomatosis. We consider that our case should be included as a case of hemangiomatosis with a benign course such as unilateral dermatomal cavernous hemangiomatosis.
