未熟児にみられた congenital self-healing reticulohistiocytosis の1例

成瀬 明子; 大霜 智子; 水野 信之; 鶴田 大輔; 堀口 裕治; 曽和 順子; 柳原 茂人; 小林 裕美; 石井 正光; 横井 俊明; 倭 和美

doi:10.11340/skinresearch.9.1_76

CASE REPORT

A Case of Congenital Self-Healing Reticulohistiocytosis in a Premature Baby

Akiko NARUSE, Tomoko OSHIMO, Nobuyuki MIZUNO, Daisuke TSURUTA, Yuji HORIGUCHI, Junko SOWA, Shigeto YANAGIHARA, Hiromi KOBAYASHI, Masamitsu ISHII, Toshiaki YOKOI, Kazumi YAMATO

Author information

Akiko NARUSE
Department of Dermatology, Osaka City University Graduate School of Medicine
Tomoko OSHIMO
Department of Dermatology, Osaka City University Graduate School of Medicine
Nobuyuki MIZUNO
Department of Dermatology, Osaka City University Graduate School of Medicine
Daisuke TSURUTA
Department of Dermatology, Osaka City University Graduate School of Medicine
Yuji HORIGUCHI
Department of Dermatology, Osaka Red Cross Hospital
Junko SOWA
Department of Dermatology, Osaka City University Graduate School of Medicine
Shigeto YANAGIHARA
Department of Dermatology, Osaka City University Graduate School of Medicine
Hiromi KOBAYASHI
Department of Dermatology, Osaka City University Graduate School of Medicine
Masamitsu ISHII
Department of Dermatology, Osaka City University Graduate School of Medicine
Toshiaki YOKOI
Department of Pediatrics, Osaka City University Graduate School of Medicine
Kazumi YAMATO
Department of Pediatrics, Osaka City University Graduate School of Medicine

Keywords: congenital self-healing reticulohistiocytosis (CSHRH), Langerhans cell histiocytosis (LCH), Langerin, Langerin-associated granule (Lag), premature baby

JOURNAL RESTRICTED ACCESS

2010 Volume 9 Issue 1 Pages 76-81

DOI https://doi.org/10.11340/skinresearch.9.1_76

Details

Abstract

We report a case of congenital self-healing reticulohistiocytosis (CSHRH) in a premature baby girl. She was born generally healthy by cesarean section at 32 weeks' gestation with a weight of 1,248g. She presented with 3 to 5mm diameter, red-brown ulcerated and crusted papules scattered on her face, limbs, and buttocks since birth. She had neither organomegaly nor lymphadenopathy. Blood and X-ray examinations showed normal findings.

Corresponding author

Register with J-STAGE for free!