Abstract
We experienced two cases of congenital cystic adenomatoid malformation (CCAM).
Case 1. A 5-year-old female was admitted to the hospital with fever and cough. Chest X-ray showed cysts with an air-fluid level in the right lower lung field. Chest CT revealed multiple cysts in the right lower lobe. We performed partial resection of the lower lobe and plication of the remaining cysts. Histologic evaluation was compatible with CCAM type 1. After the operation, she complained of fever and cough again and relapse of CCAM was observed. Right comple lower lobectomy was performed and she has been well postoperatively. Case 2. An 8-year-old male with a history of pneumonia when he was 2 years old was admitted to the hospital because of fever. Chest X-ray showed a mass shadow in the right upper lung field. Chest CT revealed a cystic mass between the superior edge of the right upper bronchus and the right apex bordering on the mediastinum. Right upper lobectomy was performed and histologic evaluation was compatible with CCAM type 1. He has been well postoperatively.