A dermoid cyst is one of the most common head and neck cystic diseases and is usually found in the submandibular area. We report a rare case of double dermoid cysts that occurred in submental and submandibular spaces at the same time in a 53-year-old woman who visited our hospital with the chief complaint of cervical swelling. MRI and CT scans revealed two tumors in the submental and submandibular spaces. The submandibular tumor had a calcified lesion. The two tumors were removed under general anesthesia. The submental tumor strongly adhered to connective tissue such as muscles and the hyoid bone. No adhesion to the surrounding tissues was observed in the submandibular tumor. Both tumors had a white muddy substance in the inside and were diagnosed as epidermal type dermoid cysts histopathologically.
