A 58-year-old woman with adenoid cystic carcinoma of the sublingual gland was reported. Adenoid cystic carcinoma is relatively rare in the sublingual gland. Our case was considered to be sublingual gland origin from surgical and histological findings. This patient was treated with surgical resection and postoperative radiation (5040 rad). She remains disease free during the postoperative period of 11 months.
