A 66-year-old female with ulcerative colitis (UC) has been treated with salazosulfapyridine, steroids and infliximab for the past 24 years since the initial diagnosis of UC. She had a good clinical course. Follow-up colonoscopy revealed multiple round, elevated lesions with a smooth surface along the ascending colon and transverse colon. The patient was diagnosed as having pneumatosis cystoides intestinalis (PCI) . There are only 40 reported cases of PCI associated with UC in Japan, including our case. We report the findings of our case with a literature review.
