Agenesis of the corpus callosum is a rare congenital anomaly. Since Reil reported the first case of this anomaly in 1812, 130 cases which were confirmed patho-anatomically, have been reported. In 1934, however, Davidoff et al. & penfield et al. had diagnosed the agenesis of corpus callosum only by pneumoencephalography, before patho-anatomical reference. Since then, 60 cases which have been diagnosed only by pneumoencephalography, were reported.
In this paper, a living case of agenesis of corpus callosum, 12 months old, male child was presented. This case showed the characteristic apperances of pneumoencephalographic findings due to agenesis of corpus callosum. It was also interesting that the patient did not have any seizures which is generally common in most of this anomaly.