Only a few cases of xanthogranuloma have been reported in oral and maxillofacial fields. In this paper, we present a case of xanthogranuloma associated with sialolithiasis. A 44-year-old male visited our hospital because of left submandibular region swelling. Salivary stone was found radiographically, in left submandibular salivary gland and duct.
Salivary gland extirpation was performed under general anesthesia. During the operation, it was very difficult to distinguish salivary gland from circumference. Pathological examination of salivary gland and mass, which seems to be lymphanode, revealed that these were xanthogranulomatous sialodenitis and xanthogranuloma respectively. Xanthomatosis, including xanthogranuloma, sometime is accompanied with hypercholesterolemia. However, serum cholestorol in this case was within normal limits. We reported a case of xanthogranuloma in submandibular region with a review of literature.
