We describe a case of lacrimal sac fistulae with left cleft lip and palate. A congenital lacrimal sac fistula is a rare disorder in which a fistulous tract connects the skin to the common canaliculus or to the lacrimal sac, located just inferior to the medial canthal angle.
A 12-year-old boy had 1) bilateral congenital lacrimal sac fistulae, 2) cleft lip and palate and 3) hypospadis. He had no paticular family history. With the patient under general anesthesia, a fusiform incision was performed, and the lacrimal sac fistulae were excised. Alveolar bone grafting was performed concurrently. Histologically, the lacrimal sac fistulae consisted of unkeratinized squamous epithelium and connective tissue with inflammatory lymphocytes. Patients with lacrimal sac fistulae, cleft lip and palate, and hypospadia have not been reported previously.
These findings suggest that lacrimal sac fistulae may be related to congenital malfusions such as cleft lip and palate.
