Cystadenocarcinoma is an uncommon salivary gland tumor that predominantly occurs in the major salivary glands rather than minor glands. We report a case of cystadenocarcinoma arising in the anterior mandibular gingiva. A 70-year-old man visited a certain hospital because of an intraoral painless tumor. The tumor was initially suspected to be an epulis and was excised with the patient under local anesthesia. The histopathological diagnosis was a cystadenocarcinoma. Eighteen months after the excision, the patient visited our hospital because of lymph node metastasis. Left radical neck dissection was performed. Metastases were histopathologically found in eight lymph nodes, one of which showed extracapsular spread.
Moreover, 4 months later, right submandibular lymph node metastasis was detected, and the patient underwent right functional neck dissection.
Unfortunately, the tumor recurred in the left side of the neck 29 months after the initial excision, and the patient was given regional radiotherapy.
